Parents' decision-making regarding whether to receive adult-onset only genetic findings for their children: Findings from the BabySeq Project.

View Abstract

PURPOSE

Most professional guidelines recommend against genetic screening for adult-onset only conditions until adulthood, yet others argue there may be benefit to disclosing such results. We explored parents' decision-making on this issue in the BabySeq Project, a clinical trial of newborn genomic sequencing.

METHODS

We conducted interviews with parents (n=24) who were given the option to receive actionable adult-onset only results for their children. Interviews explored parents' motivations to receive and reasons to decline adult-onset only genetic disease risk information, their decision-making process, and their suggestions for supporting parents in making this decision.

RESULTS

Parents noted several motivations to receive and reasons to decline adult-onset only results. Most commonly, parents cited early intervention/surveillance (n=11), implications for family heath (n=7), and the ability to prepare (n=6) as motivations to receive these results. The most common reasons to decline were protection of the child's future autonomy (n=4), negative impact on parenting (n=3), and anxiety about future disease (n=3). Parents identified a number of ways to support parents in making this decision.

CONCLUSION

Results demonstrate considerations to better support parental decision-making that aligns with their values when offering adult-onset only genetic information as it is more commonly integrated into pediatric clinical care.

Investigators
Abbreviation
Genet Med
Publication Date
2022-12-19
Page Numbers
100002
Pubmed ID
36549595
Medium
Print-Electronic
Full Title
Parents' decision-making regarding whether to receive adult-onset only genetic findings for their children: Findings from the BabySeq Project.
Authors
Pereira S, Gutierrez AM, Robinson JO, Christensen KD, Genetti CA, Blout Zawatsky CL, Hsu RL, Zettler B, Uveges MK, Parad RB, Beggs AH, Holm IA, Green RC, McGuire AL,